Transcript Document
Genomics Book (20 chapters)
Chapter 7: High throughput genetics
Chapter 8: Proteomics
Chapter 13: Genome Structure
Chapter 14: Human origin
Chapter 15: Genomics and Medicine
Chapter 18: Pharmacogenomics
Chapter 19: Genomics and Agriculture
Chapter 20: Ethical issues of genomics
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Chapter 7
High-Throughput Genetics
Applications of genomics approaches to
genetics
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Contents
Basics of forward genetics
Genomics approaches to forward genetics
Basics of reverse genetics
Genomics approaches to reverse genetics
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Background
Genetics is the study of gene function
Gene function is inferred from the resulting
phenotype when the gene is mutated
Genomics is changing the way genetics is
performed
Global, high-throughput approaches
Genomics approaches are being applied to
both forward and reverse genetics
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Forward and reverse genetics
Forward genetics starts with identification of
interesting mutant phenotype
Then aims to discover the function of genes
defective in mutants by chromosome walking
Reverse genetics starts with a known gene and
alters its function by transgenic technology
Then aims to determine the role of the gene
from the effects on the organism
This chapter focuses on applications of
genomics to genetics in model organisms
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Basics of forward genetics
Forward genetics usually starts with
mutagenesis of organism
Can use chemicals
e.g., ethyl methyl sulfonate (EMS)
Or can use radiation
e.g., X rays
Then screen progeny of mutagenized
individuals for phenotypes of interest
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Phenotype
Empirical definition: features that are different
from those of the wild type (normal)
Can be something visible
e.g., change in hair color or anatomy
Or may require invasive analysis
e.g., different mobility of enzyme during
electrophoresis
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Mouse hair-color mutant
Beige
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Drosophila anatomical mutant
Mutant with legs
instead of antennae
wild
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Genetic analysis
First step in analysis of mutants: precisely
describe phenotype
Basis of predicting gene function: identify
precisely what has malfunctioned (wrong) in
the mutant
That is what the gene product does in the wild
type
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Phenotype to gene function
Example: mouse
Small-eye mutant
Gene codes for Pax6
transcription factor
Required for normal
eye development
Same transcription
factor required for eye
development in
humans and fruit flies
Poor rat
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Genetic screens
For diploid organisms
Two chromosomes
Mutagenesis performed
Then mutagenized individuals are mated or
self-crossed
Screen progeny for mutant phenotypes
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Recessive traits
Recessive trait
Normally loss-offunction mutation
When heterozygous
parents are crossed, the
mutant phenotype
appears in 1/4 of the
progeny
homozygous heterozygous homozygous
wildtype
mutant
no
phenotype
no
phenotype
mutant
phenotype
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Dominant traits
Dominant trait
Normally gain-offunction mutation
When heterozygous
parents are crossed, the
mutant phenotype
appears in 3/4 of the
progeny
homozygous heterozygous homozygous
wildtype
mutant
no
phenotype
mutant
phenotype
mutant
phenotype
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Genomics applied to genetics
Genomics characterized by the following:
High throughput
Using automation to speed up a process
Global approach
All genes in genome
Applied to both forward and reverse genetics
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Genomics and forward genetics
High-throughput genetic screens
Candidate-gene approach
To go from phenotype to gene
Insertional mutagenesis
Loss-of-function mutation
Activation tagging
Enhancer trapping
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
High-throughput genetic screens
Some genetic screens are relatively
straightforward
e.g., For a visible phenotype like eye color
If phenotype is subtle or needs to be measured,
the screen is more time consuming
Examples
Seed weight
Behavioral traits
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Industrial setting for screens
2002Paradigm Genetics, Inc. All rights reserved. Used with permission.
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
High-throughput genetic screen
Paradigm Genetics, Inc.
performs “phenotypic
profiling”
Take measurements of
mutants’ physical and
chemical parameters
e.g., plant height, leaf
size, root density, and
nutrient utilization
Different developmental
times: compare to wild
type
2002Paradigm Genetics, Inc. All rights reserved. Used with permission.
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
From phenotype to gene
Once an interesting
mutant is found and
characterized, we want chromosome
to find the gene in
which the mutant
occurred
Positional cloning
contig
candidate genes mutation
First use genetic
mapping
Then use chromosome
walking
Needle in hay stack
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Candidate-gene approach
If the mutated gene is
localized to a sequenced
region of the
chromosome, then look
for genes that could be
involved in the process
under study
Last step: confirm gene
identification
Rescue of phenotype
Mutations in same
gene in different alleles Tau mutation in circadian rhythm
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Insertional mutagenesis
Alternative to chromosome walking
To reduce time and effort required to identify
mutant gene
Insert piece of DNA that disrupts genes
Inserts randomly in chromosomes
Make collection of individuals
Each with insertion in different place
Screen collection for phenotypes
Use inserted DNA to identify mutated gene
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Insertional mutagens
Transposable elements
Mobile elements jump from introduced DNA
e.g., P elements in Drosophila
Or start with a small number of nonautonomous
elements
Mobilize by introducing active element
e.g., AC/DS elements in plants
Single-insertion elements
e.g., T-DNA in plants
Once insert, can’t move again
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Insertional mutagenesis in Arabidopsis
T-DNA inserts into plant
chromosome
Screen for mutations
that affect flower
formation
Make genomic library
from mutant DNA
Probe with T-DNA
Identify mutant gene
T-DNA
AGAMOUS
T-DNA
inserts
into
gene
T-DNA
probe
probe library
made from
T-DNA tagged
mutant with
T-DNA
T-DNA
sequence
DNA flanking
T-DNA to
identify gene
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Activation tagging
A variation on insertional mutagenesis
Makes gain-of-function mutations instead of
loss-of-function mutations
Potential to identify gene function not
detectable through loss-of-function screens
Useful for the following cases:
Functionally redundant genes
Genes required for viability
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Activation tagging in Arabidopsis I
Strong constitutive viral
promoter
35S enhancer
T-DNA vector
CaMV 35S
Inserted randomly
With T-DNA
When inserts are near a
gene, the following
results occur:
Activation
Constitutive expression
Can result in abnormal
phenotype
35S enhancer
gene X
constitutive expression of gene X
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Activation tagging in Arabidopsis II
Examples of mutant
phenotypes found in
activation-tagging screen
In an activation-tagging
experiment carried out by
Detlef Weigel’s laboratory at
the Salk Institute, many
different abnormal
phenotypes were observed
for Arabidopsis. Among the
genes that were activated
were Flowering Locus T
(FT), which controls
flowering time, and genes
that control plant growth and
leaf shape.
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Enhancer trapping
Type of insertional mutagenesis
Used to find genes with interesting expression
patterns
Insert carries a reporter gene
Expresses foreign protein
No effect on organism
Enhancer trap
Has minimal promoter in front of reporter gene
Enhancer near point of insertion acts on it
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
By chance it will go to right place
Enhancer
Need very large population to increase your chances
Not good for all genes! Randon=m event.
Need targeted approach!
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Enhancer trapping in Drosophila I
Use transposon P element
Carries reporter gene
b-galactosidase
Hops into genome
When lands near
enhancer, activates gene
expression
Expression similar to that
of neighboring gene
enhancer
P element recognition sites
b-galactosidase
P element vector
enhancer
gene Y
b-galactosidase
gene Y
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Enhancer trapping in Drosophila II
Reporter gene: Green
Fluorescent Protein
(GFP)
The enhancer trap has
inserted into a gene
expressed in part of the
fly eye
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Gene trapping
Similar to enhancer
trapping
Instead of minimal
promoter has splice
acceptor site (AG)
before reporter gene
Expressed only when
correctly spliced
Usually causes gene
disruption as well
GT
AG
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Basics of reverse genetics
To find out the function of a known gene
Reverse genetics starts with known genes
e.g., from genomic sequencing
Goal: to determine function through targeted
modulation of gene activity
Decrease
Increase
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Ways to modulate gene activity
Delete gene
Homologous recombination
Works well in yeast
Can be done in mouse and flies not plants
Interfere with transcription
Antisense RNA
Interfering RNA (RNAi)
Identify gene affected by mutagenesis
Insertional or chemical
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Reverse-genetics example
Gene that encodes
muscle-specific
transcription factor in
mouse
Myogenin required
Homologous
recombination used to
delete gene
Mice born, but can’t
make muscle
neo
targeting vector
Tk
genome locus
myogenin
selection
neo
product of homologous recombination
selectable marker disrupts
myogenin gene
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
RNAi and antisense RNA
Double-stranded RNA able to disrupt gene
expression
Cells have machinery that destroy doublestranded RNA: viruses/ cDNA
Appears to be basis for the following:
Interfering RNA (RNAi)
Double-stranded RNA introduced into cells
Antisense RNA
Introduce complementary RNA
Forms double-stranded RNA in cells
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
RNAi mechanism I
RNAi probably depends on a system used to
detect the following:
Double-stranded (ds) RNA viruses
Other abnormal gene expression
Initially characterized in the following:
Fungus
Quelling in Neurospora
Plants
Resistance to spread of virus
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
RNAi mechanism II
Cellular RNase
recognizes dsRNA
Cleaves to small (23 bp)
fragments
Fragments hybridize to
transcripts
RNA-dependent RNA
polymerase forms
dsRNA
RISC nuclease chews up
dsRNA
RNase
RNApol
RISC
(RNA induced silencing complex)
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Systematic RNAi screens
In the roundworm, C. elegans, RNAi is easy to do
Soak in solution of dsRNA
Feed bacteria expressing dsRNA
Or inject dsRNA
Makes systematic RNAi screens possible
~ 75% of time, RNAi gives a reduction in RNA levels
(Not 100% silencing but leaky)
Has been used to reduce expression of genes
On particular chromosomes, or
Expressed at a particular developmental time
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
RNAi on all genes on chromosome
Goal: In C. elegans,
determine function of all
2,300 genes on
chromosome III
RNAi constructs made
for each gene
Worms microinjected
with double-stranded
RNA
predicted ORF
T7
T3
construct with
promoter sequence
add T3 + T7
polymerase
dsRNA
Dr. A. Hyman
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Phenotypes found in RNAi screen
Wild type
RNAi embryos
Pronuclear/nuclear
appearance
(phenotypic class B1)
Pronuclear migration
(phenotypic class C1)
Cytokinesis
(phenotypic class C6)
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
RNAi screen of embryonic genes
Microarray analysis identified genes active in
early embryogenesis
Used RNAi to target each gene
Worms injected with RNAi construct
Progeny tested for phenotypes
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Wild-type C. elegans embryogenesis
QuickTime™ and a
Motion JPEG B decompressor
are needed to see this picture.
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Effects of RNAi on actin
QuickTime™ and a
Motion JPEG A decompressor
are needed to see this picture.
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Finding genes in libraries of mutants
cDNA
Goal: Find known genes disrupted in
collections of mutants
Screening of functional-genomics libraries
Can be used for mutations that affect lethality
or fertility
Screen heterozygotes
Can either use PCR to identify mutations in a
particular gene or sequence flanking sequences
of all inserts
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Screening an insertion library
(Insertion in promoter region)
PCR used to find
insertion
One primer
complementary to insert
Other primer
complementary to gene
If get an amplification
product then you have
insertion
Sequence product for
exact location
PCR primers
insert
gene Z
PCR amplification
insert
gene Z
+
–
amplification product
on gel indicates
presence of insert
near gene
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
TILLING
Method for finding mutations produced by
chemical mutagens in specific genes
Chemical mutagenesis
Usually produces point mutations
Generally gives more subtle phenotypes than
insertions
e.g., hypomorphs, temperature sensitive mutants
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
TILLING in Arabidopsis I
EMS used to
mutagenize Arabidopsis
Grow individual
mutagenized lines
Make primers flanking
gene of interest
Amplify using PCR
EMS
mutagenize
seed
gene Z
WT
gene Z
mutant
PCR amplification
from wild type
and mutant
WT
mutant
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
TILLING in Arabidopsis II
Denature DNA from
pools of mutant lines
Allow to hybridize to
wild-type DNA
Detect mismatches in
hybridized DNA
Denaturing HPLC
Cel I enzyme cuts at
mismatches
Sequence to identify site
of mutation
ATGCGGACTG
|||||| ||| +
TACGCCGGAC
ATGCGG
||||||
TACGCC
Cel 1
CTG
|||
GAC
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Summary I
Forward genetics
Mutation to gene function
Genetic screens
Cloning genes identified in screens
Genomics approaches to forward genetics
High-throughput genetic screens
Insertional mutagenesis
Activation tagging
Enhancer trapping and gene trapping
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458
Summary II
Reverse genetics
From gene to function
Genomics approaches to reverse genetics
RNAi screens
Identifying mutations in insertional libraries
TILLING
© 2005 Prentice Hall Inc. / A Pearson Education Company / Upper Saddle River, New Jersey 07458